BANF1

protein-coding

BAF nuclear assembly factor 1

Gene summary

The protein encoded by this gene was first identified by its ability to protect retroviruses from intramolecular integration and therefore promote intermolecular integration into the host cell genome. The protein forms a homodimer which localizes to both the nucleus and cytoplasm and is specifically associated with chromosomes during mitosis. This protein binds to double stranded DNA in a non-specific manner and also binds to LEM-domain containing proteins of the nuclear envelope. This protein is thought to facilitate nuclear reassembly by binding with both DNA and inner nuclear membrane proteins and thereby recruit chromatin to the nuclear periphery. Alternative splicing results in multiple transcript variants encoding the same protein.[provided by RefSeq, Jan 2009]

MANE transcript

NM_003860.4

Inheritance

AR, AD

ClinVar variants

U:4B:1

Top phenotype

Nestor-Guillermo progeria syndrome

gnomAD constraint

pLI —, LoF o/e 0

Max pathogenic AF

—

Genomic locus

chr11:66,002,228-66,004,149

External References & Databases

Transcript & Mutation Effects

hg38 • Region Span ~1.9 kb
Loading mutation effect viewer...

GenCC Phenotypes & Disease Associations

Curated gene-disease validity assertions and inheritance patterns

Nestor-Guillermo progeria syndromeSUPPORTIVE

Inheritance Pattern: AR

Disease ID:MONDO:0013523

Submitter: Orphanet

Nestor-Guillermo progeria syndromeMODERATE

Inheritance Pattern: AR

Disease ID:MONDO:0013523

Submitter: G2P

Nestor-Guillermo progeria syndromeLIMITED

Inheritance Pattern: AR

Disease ID:MONDO:0013523

Submitter: ClinGen

The BANF1 gene is located on chromosome 11 at 11q13.1 and encodes the barrier to autointegration nuclear assembly factor 1 protein, a non-specific DNA-binding protein that plays key roles in mitotic nuclear reassembly, chromatin organization, DNA damage response, gene expression and intrinsic immunity against foreign DNA. BANF1 was first reported in relation to autosomal recessive Néstor-Guillermo Progeria Syndrome (NGPS) in 2011 (Puente et al., PMID: 21549337;). NGPS is a unique progeria with a relatively long lifespan with features such as signs of aging, growth delay, reduced subcutaneous fat, decreased diameter of limbs, and stiffening of the joints. Per criteria outlined by the ClinGen Lumping and Splitting Working Group, we found clear differences in inheritance pattern and phenotypic variability between the following disease entities which have therefore been split: autosomal recessive NGPS and BANF1-related neurodevelopmental disorder. The split curation for autosomal dominant BANF1-related neurodevelopmental disorder has been curated separately. One missense variant (possible founder variant in Spanish families) that has been reported in 3 probands in 2 publications (PMIDs: 21549337, 32783369) is included in this curation. The mechanism of pathogenicity appears to be loss-of-function. This gene-disease relationship is also supported by experimental evidence, including protein interaction and biochemical functional evidence, specifically interaction evidence with lamin, and function in DNA stability/repair activity (PMIDs: 36039758, 33660778). In summary, there is limited evidence supporting the relationship between BANF1 and autosomal recessive NGPS. Although more evidence is needed to support a causal role, no convincing evidence has emerged that contradicts the gene-disease relationship. This classification was approved by the ClinGen Syndromic Disorders GCEP on the meeting date April 3rd, 2024 (SOP Version 10).

neurodevelopmental disorderLIMITED

Inheritance Pattern: AD

Disease ID:MONDO:0700092

Submitter: PanelApp Australia

hereditary peripheral neuropathyLIMITED

Inheritance Pattern: AD

Disease ID:MONDO:0020127

Submitter: PanelApp Australia

Nestor-Guillermo progeria syndromeMODERATE

Inheritance Pattern: AR

Disease ID:MONDO:0013523

Submitter: PanelApp Australia

Nestor-Guillermo progeria syndromeLIMITED

Inheritance Pattern: Unknown

Disease ID:MONDO:0013523

Submitter: Labcorp Genetics (formerly Invitae)

Nestor-Guillermo progeria syndromeLIMITED

Inheritance Pattern: AR

Disease ID:MONDO:0013523

Submitter: Ambry Genetics

Clinical Genomic Database (CGD)

Nestor-Guillermo progeria syndromeAR

Manifestation: Cardiovascular; Craniofacial; Dermatologic; Musculoskeletal

Intervention: General

Rationale: Genetic knowledge may be beneficial related to issues such as selection of optimal supportive care, informed medical decision-making, prognostic considerations, and avoidance of unnecessary testing

Refs: 21932319; 21549337Source: CGD (NHGRI)

ClinVar Associated Diseases & Phenotypes

Reported disease conditions connected to BANF1 variants in ClinVar

2 Conditions Cataloged
Nestor-Guillermo progeria syndromeTotal: 3
not providedTotal: 1

ClinVar Variants & Pathogenicity by Type

Statistics based on transcript NM_003860.4. Only rare variants are included.

We include only reliable ClinVar variants with their consequences to MANE Select, MANE Plus Clinical transcripts, or transcripts with TSL equal to 1. Click a count to filter the variants table below.

Slight differences between displayed counts and ClinVar may occur due to a different transcript/consequence chosen by our variant effect predictor, or because we classify Benign/Likely benign as Likely benign and Pathogenic/Likely pathogenic as Likely pathogenic.

EffectPLPVUSLBBSum
synonymous
1
clinvar
1
clinvar
2
missense
1
clinvar
1
nonsense
0
start loss
0
frameshift
0
splice donor/acceptor (+/-2bp)
2
clinvar
2
Total004015
Loading ClinVar variants...

Transcript Catalog

Annotated transcript isoforms across RefSeq and Ensembl databases

Showing 4 of 60 transcripts
Transcript IDSourceProtein IDCoding ExonsMANE Status
NM_003860.4RefSeqNP_003851.12MANE Select
ENST00000312175.7EnsemblENSP00000310275.22MANE Select
NM_001143985.2RefSeqNP_001137457.12Standard
NM_001440618.1RefSeqNP_001427547.12Standard

Gene Ontology (GO) Annotations & Pathways

Biological processes, molecular functions, cellular components and pathways

Pathways ConsensusPathDB

  • Disease
  • HIV Life Cycle
  • Host Interactions of HIV factors
  • HIV Infection
  • Vpr-mediated nuclear import of PICs

Biological Process

  • mitotic nuclear envelope reassembly
  • response to virus
  • DNA integration
  • negative regulation of viral genome replication
  • nuclear transport

Molecular Function

  • DNA binding
  • protein binding
  • protein C-terminus binding
  • enzyme binding
  • identical protein binding

Cellular Component

  • condensed chromosome
  • nucleus
  • nuclear envelope
  • nucleoplasm
  • cytoplasm

gnomAD Constraint

Source: gnomAD

Gene type
protein_coding
Transcript type
protein_coding
Transcript
ENST00000312175
Coding exons
2
Length
2071
Individuals with no LoFs
125744
Homozygous LoFs
0
Heterozygous LoFs
4
Defined
125748
p
0.0000159
Z-ScoreObservedExpectedObserved/ExpectedMutation RateTotal Possible
Missense1.432352.00.4420.00000324578
Missense (PolyPhen)316.3140.1839222
Synonymous-0.7132621.81.190.00000145175
Loss of Function1.7103.410.001.97e-737

Population LoF Frequency

PopulationCAFp-valueStatus
African00.0absent
Latino/Admixed American0.0000290.000029rare
Ashkenazi Jewish00.0absent
East Asian00.0absent
Finnish00.0absent
European (Non-Finnish)0.0000260.000026rare
South Asian00.0absent
Other00.0absent

dbNSFP Gene Annotations

Source: dbNSFP

Function
FUNCTION: Plays fundamental roles in nuclear assembly, chromatin organization, gene expression and gonad development. May potently compress chromatin structure and be involved in membrane recruitment and chromatin decondensation during nuclear assembly. Contains 2 non-specific dsDNA-binding sites which may promote DNA cross-bridging. {ECO:0000269|PubMed:12163470}.; FUNCTION: (Microbial infection) In case of poxvirus infection, has an antiviral activity by blocking viral DNA replication. {ECO:0000269|PubMed:18005698}.;
Disease
DISEASE: Nestor-Guillermo progeria syndrome (NGPS) [MIM:614008]: An atypical progeroid syndrome characterized by normal development in the first years of life, later followed by the emergence of generalized lipoatrophy, severe osteoporosis, and marked osteolysis. The atrophic facial subcutaneous fat pad and the marked osteolysis of the maxilla and mandible result in a typical pseudosenile facial appearance with micrognathia, prominent subcutaneous venous patterning, a convex nasal ridge, and proptosis. Cognitive development is completely normal. Patients do not have cardiovascular dysfunction, atherosclerosis, or metabolic anomalies. {ECO:0000269|PubMed:21549337}. Note=The disease is caused by mutations affecting the gene represented in this entry.;

Recessive Scores

pRec
0.375

Intolerance Scores

LoFtool
0.488
RVIS EVS
-0.01
RVIS percentile EVS
52.85

Essentials

Essential (CRISPR)
E
Essential (gene trap)
E
Indispensability pred.
E
Indispensability score
0.781

Gene Damage Prediction

AllRecessiveDominant
MendelianLowLowLow
Primary ImmunodeficiencyLowLowLow
CancerLowLowLow
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